Introduction: Congenital anterior urethro-cutaneous fistula (CAUF) is an extremely rare abnormality that can register as a malformative entity with hypospadias or cord, or present in an isolated form. Purpose: The purpose of our observation is to present our surgical management of a case of CAUF. Observation: We describe the clinical case of a 10-year-old patient, who presented with CAUF in the ventral mid-penile position, diagnosed at birth. He underwent urethroplasty using Mathieu's technique with simple consequences. The uretral catheter removed at 21 days post-surgery. No complications at 30 days post-operatively. Discussion: CAUF is an extremely rare condition. The etiology is unknown, and several pathogenetic theories have been used to explain its causes.The clinical characteristics are not well defined. An overall assessment of the disease can be carried out in search of other associated abnormalities. CAUF also associated with other congenital anomalies, such as deficient distal urethra, distal hypospadias, ventral penile curvature, anorectal malformations, stenosed bulbar urethra, epispadic urethral duplication, and megalourethra. Abdominal ultrasound and cystoscopy and/or cystography may be performed Therapeutically, surgery remains the only treatment, it includes many methods of surgical repair. Mathieu's technique is the most practiced and gives excellent results. Conclusion: CAUF is a rare anomaly, which must be diagnosed in order to be treated. Surgical treatment offers satisfactory results.
| Published in | International Journal of Clinical Urology (Volume 6, Issue 2) |
| DOI | 10.11648/j.ijcu.20220602.18 |
| Page(s) | 119-121 |
| Creative Commons |
This is an Open Access article, distributed under the terms of the Creative Commons Attribution 4.0 International License (http://creativecommons.org/licenses/by/4.0/), which permits unrestricted use, distribution and reproduction in any medium or format, provided the original work is properly cited. |
| Copyright |
Copyright © The Author(s), 2022. Published by Science Publishing Group |
Fistula, Urethrocutaneous, Congenital, Urethroplasty
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APA Style
Smith Giscard Olagui, Steevy Ndang Ngou Milama, Christelle Mezene, Dimitri Mbethe, Adrien Mougougou, et al. (2022). Congenital Anterior Urethrocutaneous Fistula: A Case Report and Review of Literature. International Journal of Clinical Urology, 6(2), 119-121. https://doi.org/10.11648/j.ijcu.20220602.18
ACS Style
Smith Giscard Olagui; Steevy Ndang Ngou Milama; Christelle Mezene; Dimitri Mbethe; Adrien Mougougou, et al. Congenital Anterior Urethrocutaneous Fistula: A Case Report and Review of Literature. Int. J. Clin. Urol. 2022, 6(2), 119-121. doi: 10.11648/j.ijcu.20220602.18
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author = {Smith Giscard Olagui and Steevy Ndang Ngou Milama and Christelle Mezene and Dimitri Mbethe and Adrien Mougougou and Gloire Allogho Mbouye and Mariette Nsa Bidzo and Fatou Moutsinga and Jean Placide Owono Mbouengou and Eric Jacob Benizri},
title = {Congenital Anterior Urethrocutaneous Fistula: A Case Report and Review of Literature},
journal = {International Journal of Clinical Urology},
volume = {6},
number = {2},
pages = {119-121},
doi = {10.11648/j.ijcu.20220602.18},
url = {https://doi.org/10.11648/j.ijcu.20220602.18},
eprint = {https://article.sciencepublishinggroup.com/pdf/10.11648.j.ijcu.20220602.18},
abstract = {Introduction: Congenital anterior urethro-cutaneous fistula (CAUF) is an extremely rare abnormality that can register as a malformative entity with hypospadias or cord, or present in an isolated form. Purpose: The purpose of our observation is to present our surgical management of a case of CAUF. Observation: We describe the clinical case of a 10-year-old patient, who presented with CAUF in the ventral mid-penile position, diagnosed at birth. He underwent urethroplasty using Mathieu's technique with simple consequences. The uretral catheter removed at 21 days post-surgery. No complications at 30 days post-operatively. Discussion: CAUF is an extremely rare condition. The etiology is unknown, and several pathogenetic theories have been used to explain its causes.The clinical characteristics are not well defined. An overall assessment of the disease can be carried out in search of other associated abnormalities. CAUF also associated with other congenital anomalies, such as deficient distal urethra, distal hypospadias, ventral penile curvature, anorectal malformations, stenosed bulbar urethra, epispadic urethral duplication, and megalourethra. Abdominal ultrasound and cystoscopy and/or cystography may be performed Therapeutically, surgery remains the only treatment, it includes many methods of surgical repair. Mathieu's technique is the most practiced and gives excellent results. Conclusion: CAUF is a rare anomaly, which must be diagnosed in order to be treated. Surgical treatment offers satisfactory results.},
year = {2022}
}
TY - JOUR T1 - Congenital Anterior Urethrocutaneous Fistula: A Case Report and Review of Literature AU - Smith Giscard Olagui AU - Steevy Ndang Ngou Milama AU - Christelle Mezene AU - Dimitri Mbethe AU - Adrien Mougougou AU - Gloire Allogho Mbouye AU - Mariette Nsa Bidzo AU - Fatou Moutsinga AU - Jean Placide Owono Mbouengou AU - Eric Jacob Benizri Y1 - 2022/12/08 PY - 2022 N1 - https://doi.org/10.11648/j.ijcu.20220602.18 DO - 10.11648/j.ijcu.20220602.18 T2 - International Journal of Clinical Urology JF - International Journal of Clinical Urology JO - International Journal of Clinical Urology SP - 119 EP - 121 PB - Science Publishing Group SN - 2640-1355 UR - https://doi.org/10.11648/j.ijcu.20220602.18 AB - Introduction: Congenital anterior urethro-cutaneous fistula (CAUF) is an extremely rare abnormality that can register as a malformative entity with hypospadias or cord, or present in an isolated form. Purpose: The purpose of our observation is to present our surgical management of a case of CAUF. Observation: We describe the clinical case of a 10-year-old patient, who presented with CAUF in the ventral mid-penile position, diagnosed at birth. He underwent urethroplasty using Mathieu's technique with simple consequences. The uretral catheter removed at 21 days post-surgery. No complications at 30 days post-operatively. Discussion: CAUF is an extremely rare condition. The etiology is unknown, and several pathogenetic theories have been used to explain its causes.The clinical characteristics are not well defined. An overall assessment of the disease can be carried out in search of other associated abnormalities. CAUF also associated with other congenital anomalies, such as deficient distal urethra, distal hypospadias, ventral penile curvature, anorectal malformations, stenosed bulbar urethra, epispadic urethral duplication, and megalourethra. Abdominal ultrasound and cystoscopy and/or cystography may be performed Therapeutically, surgery remains the only treatment, it includes many methods of surgical repair. Mathieu's technique is the most practiced and gives excellent results. Conclusion: CAUF is a rare anomaly, which must be diagnosed in order to be treated. Surgical treatment offers satisfactory results. VL - 6 IS - 2 ER -
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